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4-hydroxyphenylpyruvate dioxygenase inhibitor

Nitisinone

Brand names: Orfadin, Nityr

Adult dose

Dose: Tyrosinaemia type 1: 1 mg/kg/day in 2 divided doses. Alkaptonuria: 10mg OD
Route: PO
Frequency: OD-BD

Clinical pearls

  • HT-1 (life-saving) and alkaptonuria; specialist metabolic
  • Strict tyrosine/phenylalanine restricted diet mandatory

Contraindications

  • Hypersensitivity

Side effects

  • Thrombocytopenia / leucopenia
  • Photophobia / corneal opacity (high tyrosine — strict diet required)
  • Conjunctivitis

Interactions

  • CYP2C9 substrates (raised levels)
  • Drugs requiring tyrosine

Monitoring

  • Tyrosine levels
  • FBC
  • LFTs
  • Ophthalmic

Reference: BNF; NICE TA755; SmPC; https://bnf.nice.org.uk/drugs/nitisinone/. Verify against your local formulary and the latest BNF before prescribing.

Related

Curated clinical cross-links plus same-class fallbacks.