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Carbamoyl phosphate synthetase 1 activator (urea cycle defect)

Carglumic acid

Brand names: Carbaglu

Adult dose

Dose: Acute hyperammonaemia: 100–250mg/kg/day in divided doses; Maintenance: 10–100mg/kg/day per response
Route: Oral / dispersed
Frequency: BD–QDS

Clinical pearls

  • N-acetylglutamate synthetase (NAGS) deficiency, organic acidaemias (propionic, methylmalonic, isovaleric)
  • BIMDG urea cycle / organic acidaemia guidelines
  • UK metabolic centre supervision

Contraindications

  • Hypersensitivity

Side effects

  • Sweating
  • Headache
  • Anaemia
  • Increased liver enzymes
  • GI upset

Monitoring

  • Ammonia
  • Plasma amino acids
  • Organic acids
  • LFTs
  • Growth

Reference: BNF; BIMDG; ESPGHAN; SmPC; https://bnf.nice.org.uk/drugs/carglumic-acid/. Verify against your local formulary and the latest BNF before prescribing.

Related

Curated clinical cross-links plus same-class fallbacks.